Echocardiographic Diagnosis and Treatment of ALCAPA Syndrome in a Pregnant Woman: A Case Report
Abstract
In this report, we present the case of a 21-year-old woman diagnosed with ALCAPA syndrome during pregnancy, based on echocardiographic findings. We also review the diagnostic process, pregnancy management, and treatment of the patient.
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2. Cantador AA, Siqueira DED, Guillaumon AT. Anomaly in the Embryogenesis of the Aorta associated with Subclavian Steal Phenomenon. Ann Vasc Surg. 2019;60:477.e11-.e13.
3. Tsoutsinos A, Mitropoulos F, Trapali C, Papagiannis J. Anomalous origin of the left coronary artery from the pulmonary artery associated with an accessory atrioventricular pathway and managed successfully with surgical and interventional electrophysiological treatment: a case report. J Med Case Rep. 2011;5:384-.
4. Wesselhoeft H, Fawcett JS, Johnson AL. Anomalous origin of the left coronary artery from the pulmonary trunk. Its clinical spectrum, pathology, and pathophysiology, based on a review of 140 cases with seven further cases. Circulation. 1968;38(2):403-25.
5. Arciniegas E, Farooki ZQ, Hakimi M, Green EW. Management of anomalous left coronary artery from the pulmonary artery. Circulation. 1980;62(2 Pt 2):I180-9.
6. Peña E, Nguyen ET, Merchant N, Dennie C. ALCAPA Syndrome: Not Just a Pediatric Disease. RadioGraphics. 2009;29(2):553-65.
7. Ginde S, Earing MG, Bartz PJ, Cava JR, Tweddell JS. Late complications after Takeuchi repair of anomalous left coronary artery from the pulmonary artery: case series and review of literature. Pediatr Cardiol. 2012;33(7):1115-23.
8. Jinmei Z, Yunfei L, Yue W, Yongjun Q. Anomalous origin of the left coronary artery from the pulmonary artery (ALCAPA) diagnosed in children and adolescents. J Cardiothorac Surg. 2020;15(1):90.
9. Nielsen HB, Perko M, Aldershvile j, Saunama¨ki k. Cardiac Arrest During Exercise: Anomalous Left Coronary Artery from the Pulmonary Trunk. Scand Cardiovasc J. 1999;33(6):369-71.
10. Lin L, Murakami T, Shiono J, Horigome H. Vascular Network Inside the Heart - Collateral Flow on Color Doppler Echo in a Child With Anomalous Left Coronary Artery From the Pulmonary Artery (ALCAPA). Circ J. 2018;82(10):2680-1.
11. Kanoh M, Inai K, Shinohara T, Shimada E, Shimizu M, Tomimatsu H, et al. Pregnancy and delivery outcomes from patients with repaired anomalous origin of the left coronary artery from the pulmonary artery. J Obstet Gynaecol Res. 2018;44(5):899-906.
12. Bhimani SA, Najm HK, Komarlu R. Life saved and a lesson learned-anomalous origin of the left coronary artery from pulmonary artery in pregnancy. Cardiol Young. 2022;32(4):662-4.
13. Beyaz MO, Coban S, Ulukan MO, Dogan MS, Erol C, Saritas T, et al. Current Strategies for the Management of Anomalous Origin of Coronary Arteries from the Pulmonary Artery. Heart Surg Forum. 2021;24(1):E065-e71.
2. Cantador AA, Siqueira DED, Guillaumon AT. Anomaly in the Embryogenesis of the Aorta associated with Subclavian Steal Phenomenon. Ann Vasc Surg. 2019;60:477.e11-.e13.
3. Tsoutsinos A, Mitropoulos F, Trapali C, Papagiannis J. Anomalous origin of the left coronary artery from the pulmonary artery associated with an accessory atrioventricular pathway and managed successfully with surgical and interventional electrophysiological treatment: a case report. J Med Case Rep. 2011;5:384-.
4. Wesselhoeft H, Fawcett JS, Johnson AL. Anomalous origin of the left coronary artery from the pulmonary trunk. Its clinical spectrum, pathology, and pathophysiology, based on a review of 140 cases with seven further cases. Circulation. 1968;38(2):403-25.
5. Arciniegas E, Farooki ZQ, Hakimi M, Green EW. Management of anomalous left coronary artery from the pulmonary artery. Circulation. 1980;62(2 Pt 2):I180-9.
6. Peña E, Nguyen ET, Merchant N, Dennie C. ALCAPA Syndrome: Not Just a Pediatric Disease. RadioGraphics. 2009;29(2):553-65.
7. Ginde S, Earing MG, Bartz PJ, Cava JR, Tweddell JS. Late complications after Takeuchi repair of anomalous left coronary artery from the pulmonary artery: case series and review of literature. Pediatr Cardiol. 2012;33(7):1115-23.
8. Jinmei Z, Yunfei L, Yue W, Yongjun Q. Anomalous origin of the left coronary artery from the pulmonary artery (ALCAPA) diagnosed in children and adolescents. J Cardiothorac Surg. 2020;15(1):90.
9. Nielsen HB, Perko M, Aldershvile j, Saunama¨ki k. Cardiac Arrest During Exercise: Anomalous Left Coronary Artery from the Pulmonary Trunk. Scand Cardiovasc J. 1999;33(6):369-71.
10. Lin L, Murakami T, Shiono J, Horigome H. Vascular Network Inside the Heart - Collateral Flow on Color Doppler Echo in a Child With Anomalous Left Coronary Artery From the Pulmonary Artery (ALCAPA). Circ J. 2018;82(10):2680-1.
11. Kanoh M, Inai K, Shinohara T, Shimada E, Shimizu M, Tomimatsu H, et al. Pregnancy and delivery outcomes from patients with repaired anomalous origin of the left coronary artery from the pulmonary artery. J Obstet Gynaecol Res. 2018;44(5):899-906.
12. Bhimani SA, Najm HK, Komarlu R. Life saved and a lesson learned-anomalous origin of the left coronary artery from pulmonary artery in pregnancy. Cardiol Young. 2022;32(4):662-4.
13. Beyaz MO, Coban S, Ulukan MO, Dogan MS, Erol C, Saritas T, et al. Current Strategies for the Management of Anomalous Origin of Coronary Arteries from the Pulmonary Artery. Heart Surg Forum. 2021;24(1):E065-e71.
| Files | ||
| Issue | Vol 20 No 1 (2025) | |
| Section | Case Report(s) | |
| DOI | https://doi.org/10.18502/jthc.v20i1.19223 | |
| Keywords | ||
| Echocardiography coronary vessel anomalies syncope pregnancy | ||
| Rights and permissions | |
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This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License. |
How to Cite
1.
Montazeri SMH, Norouzi S. Echocardiographic Diagnosis and Treatment of ALCAPA Syndrome in a Pregnant Woman: A Case Report. Res Heart Yield Transl Med. 2025;20(1):69-73.
